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Open Access
Peer-reviewed
Research Article
Activation of the ciliary kinase CDKL5 is mediated by the cyclin-dependent kinase CDK20/LF2 to control flagellar length
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Yuqing Hou ,
Contributed equally to this work with: Yuqing Hou, Oranti Ahmed Omi
Roles Conceptualization, Data curation, Formal analysis, Investigation, Visualization, Writing – original draft, Writing – review & editing
Affiliation Department of Radiology, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Oranti Ahmed Omi ,
Contributed equally to this work with: Yuqing Hou, Oranti Ahmed Omi
Roles Conceptualization, Data curation, Formal analysis, Investigation, Visualization, Writing – original draft, Writing – review & editing
Affiliation Department of Cellular Biology, University of Georgia, Athens, Georgia, United States of America
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Michael W. Stuck,
Roles Conceptualization, Data curation, Formal analysis, Investigation, Visualization, Writing – review & editing
Affiliation Program in Molecular Medicine, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Xi Cheng,
Roles Investigation, Writing – review & editing
Affiliation Department of Radiology, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Bethany Walker,
Roles Investigation, Writing – review & editing
Affiliation Department of Radiology, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Ying-Wai Lam,
Roles Formal analysis, Investigation, Writing – review & editing
Affiliation Department of Biology, University of Vermont, Burlington, Vermont, United States of America
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Anna M. Schmoker,
Roles Formal analysis, Investigation, Writing – review & editing
Current address: Biological Mass Spectrometry and Proteomics Shared Resource, Geisel School of Medicine, Dartmouth College, Hanover, New Hampshire, United States of America
Affiliation Dana-Farber Cancer Institute, Boston, Massachusetts, United States of America
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Son N. Nguyen,
Roles Formal analysis, Investigation, Writing – review & editing
Affiliation Mass Spectrometry Facility, UMass Chan Medical School, Shrewsbury, Massachusetts, United States of America
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Maria Paz Gonzalez-Perez,
Roles Formal analysis, Investigation, Writing – review & editing
Affiliation Mass Spectrometry Facility, UMass Chan Medical School, Shrewsbury, Massachusetts, United States of America
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Bryan A. Ballif,
Roles Conceptualization, Formal analysis, Investigation, Writing – review & editing
Affiliation Department of Biology, University of Vermont, Burlington, Vermont, United States of America
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Karl F. Lechtreck ,
Roles Conceptualization, Formal analysis, Funding acquisition, Investigation, Writing – original draft, Writing – review & editing
* E-mail: george.witman@umassmed.edu (GBW); lechtrek@uga.edu (KFL); gregory.pazour@umassmed.edu (GJP)
Affiliation Department of Cellular Biology, University of Georgia, Athens, Georgia, United States of America
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George B. Witman ,
Roles Conceptualization, Formal analysis, Funding acquisition, Investigation, Writing – original draft, Writing – review & editing
* E-mail: george.witman@umassmed.edu (GBW); lechtrek@uga.edu (KFL); gregory.pazour@umassmed.edu (GJP)
Affiliation Department of Radiology, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Gregory J. Pazour
Roles Conceptualization, Formal analysis, Funding acquisition, Investigation, Writing – original draft, Writing – review & editing
* E-mail: george.witman@umassmed.edu (GBW); lechtrek@uga.edu (KFL); gregory.pazour@umassmed.edu (GJP)
Affiliation Program in Molecular Medicine, UMass Chan Medical School, Worcester, Massachusetts, United States of America
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Activation of the ciliary kinase CDKL5 is mediated by the cyclin-dependent kinase CDK20/LF2 to control flagellar length
- Yuqing Hou,
- Oranti Ahmed Omi,
- Michael W. Stuck,
- Xi Cheng,
- Bethany Walker,
- Ying-Wai Lam,
- Anna M. Schmoker,
- Son N. Nguyen,
- Maria Paz Gonzalez-Perez,
- Bryan A. Ballif
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- Published: December 12, 2025
- https://doi.org/10.1371/journal.pbio.3003560