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Open Access
Peer-reviewed
Research Article
Atp7b-dependent choroid plexus dysfunction causes transient copper deficit and metabolic changes in the developing mouse brain
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Clorissa L. Washington-Hughes ,
Contributed equally to this work with: Clorissa L. Washington-Hughes, Shubhrajit Roy
Roles Conceptualization, Data curation, Formal analysis, Investigation, Methodology, Validation, Visualization, Writing – original draft
Affiliation Department of Physiology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Shubhrajit Roy ,
Contributed equally to this work with: Clorissa L. Washington-Hughes, Shubhrajit Roy
Roles Data curation, Investigation, Visualization, Writing – review & editing
Affiliation Department of Physiology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Herana Kamal Seneviratne,
Roles Data curation, Formal analysis, Investigation, Methodology, Validation, Visualization
Affiliation Department of Medicine, Division of Clinical Pharmacology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Senthilkumar S. Karuppagounder,
Roles Data curation, Formal analysis, Investigation, Visualization
Affiliations Neurodegeneration and Stem Cell Program, Institute for Cell Engineering, Johns Hopkins University School of Medicine, Baltimore, Maryland, Department of Neurology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Yulemni Morel,
Roles Investigation
Affiliation Department of Pharmaceutical Sciences, University of Maryland School of Pharmacy, Baltimore, Maryland
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Jace W. Jones,
Roles Conceptualization, Data curation, Formal analysis, Investigation, Methodology, Validation, Visualization, Writing – original draft
Affiliation Department of Pharmaceutical Sciences, University of Maryland School of Pharmacy, Baltimore, Maryland
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Alex Zak,
Roles Data curation, Formal analysis, Investigation, Methodology, Visualization
Affiliation Department of Physiology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Tong Xiao,
Roles Data curation, Formal analysis, Investigation, Methodology, Visualization, Writing – original draft
Affiliation Department of Chemistry, University of California Berkeley, California, United States of America
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Tatiana N. Boronina,
Roles Data curation, Formal analysis, Methodology, Visualization, Writing – original draft
Affiliation Department of Biological Chemistry Johns Hopkins University School of Medicine, Baltimore, Maryland
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Robert N. Cole,
Roles Conceptualization, Methodology, Supervision
Affiliation Department of Biological Chemistry Johns Hopkins University School of Medicine, Baltimore, Maryland
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Namandjé N. Bumpus,
Roles Funding acquisition, Methodology, Project administration, Supervision
Affiliation Department of Medicine, Division of Clinical Pharmacology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Christopher J. Chang,
Roles Funding acquisition, Methodology, Supervision, Writing – review & editing
Affiliations Department of Chemistry, University of California Berkeley, California, United States of America, Department of Molecular and Cell Biology, University of California Berkeley, California, Helen Wills Neuroscience Institute, University of California Berkeley, California
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Ted M. Dawson,
Roles Funding acquisition, Resources, Supervision
Affiliations Neurodegeneration and Stem Cell Program, Institute for Cell Engineering, Johns Hopkins University School of Medicine, Baltimore, Maryland, Department of Neurology, Johns Hopkins University School of Medicine, Baltimore, Maryland, Solomon H. Snyder Department of Neuroscience, Johns Hopkins University School of Medicine, Baltimore, Maryland; United States of America
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Svetlana Lutsenko
Roles Conceptualization, Funding acquisition, Methodology, Project administration, Resources, Supervision, Writing – review & editing
* E-mail: lutsenko@jhmi.edu
Affiliation Department of Physiology, Johns Hopkins University School of Medicine, Baltimore, Maryland
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Atp7b-dependent choroid plexus dysfunction causes transient copper deficit and metabolic changes in the developing mouse brain
- Clorissa L. Washington-Hughes,
- Shubhrajit Roy,
- Herana Kamal Seneviratne,
- Senthilkumar S. Karuppagounder,
- Yulemni Morel,
- Jace W. Jones,
- Alex Zak,
- Tong Xiao,
- Tatiana N. Boronina,
- Robert N. Cole
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- Published: January 10, 2023
- https://doi.org/10.1371/journal.pgen.1010558